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Chronic non-granulomatous supraglottitis: a rare and difficult disease

Published online by Cambridge University Press:  29 May 2012

L G Ledgerwood  and
P C Belafsky
L G Ledgerwood
Affiliation:
Center for Voice and Swallowing, University of California, Sacramento, USA
P C Belafsky*
Affiliation:
Center for Voice and Swallowing, University of California, Sacramento, USA
*
Address for correspondence: Dr Peter C Belafsky, Center for Voice and Swallowing, University of California, Davis, 2521 Stockton Blvd, Suite 7200, Sacramento, CA 95817, USA Fax: +1 916 703 5011 E-mail: peterb@ucdvoice.org
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Abstract

Objectives:

To examine chronic non-granulomatous supraglottitis, a rare disorder of uncertain aetiology with few reported cases in the literature.

Case reports:

We describe two cases of chronic non-granulomatous supraglottitis that led to persistent respiratory compromise. Patients underwent extensive investigation that failed to reveal a definitive diagnosis.

Conclusion:

In patients suffering from chronic inflammation of the supraglottic larynx without evidence of infection, neoplasm or granulomatous disease, many disorders must be ruled out in order to diagnose chronic non-granulomatous supraglottitis, which is a diagnosis of exclusion. We review the literature on this rare entity, discuss current management strategies, and suggest an algorithm for diagnostic investigation.

Keywords

EpiglottitisDysphagiaDyspneaHydroxychloroquine
Type
Clinical Records
Information
The Journal of Laryngology & Otology , Volume 126 , Issue 8 , August 2012 , pp. 854 - 857
Copyright
Copyright © JLO (1984) Limited 2012

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Footnotes

Presented as a poster at the American Laryngological Association as part of the Combined Otolaryngological Spring Meetings, 27–28 April 2011, Chicago, Illinois, USA

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