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Pulmonary diffuse arterial calcifications: a very rare complication in the recipient of a twin-to-twin transfusion syndrome

Published online by Cambridge University Press:  01 August 2009

Rania Bassil Eter ,
Yves Dulac  and
Philippe Acar
Rania Bassil Eter
Affiliation:
Department of Pediatric Cardiology, Children’s Hospital, Toulouse, France
Yves Dulac*
Affiliation:
Department of Pediatric Cardiology, Children’s Hospital, Toulouse, France
Philippe Acar
Affiliation:
Department of Pediatric Cardiology, Children’s Hospital, Toulouse, France
*
Correspondence to: Dr Yves Dulac, Cardiologie Pédiatrique, Hôpital des Enfants, 330 av de Grande-Bretagne, 31000 Toulouse, France. Tel: +33 5 34 55 85 96; Fax: +33 5 34 55 86 63; E-mail: dulac.y@chu-toulouse.fr
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Abstract

The syndrome of twin-to-twin transfusion is known potentially to be associated with the development of right ventricular obstruction, albeit rarely at supravalvar levels, in the recipient twin. We report the case of a recipient twin with diffuse hypoplasia and calcification of the pulmonary arterial tree, confirmed by postnatal thoracic angioscan. When aged 2 years, the child was moderately symptomatic with mild cyanosis, in spite of suprasystemic right ventricular systolic pressure as revealed by follow-up echocardiography.

Keywords

Monochorionic twinsright ventricular outflow tract obstructionendothelin-1
Type
Brief Reports
Information
Cardiology in the Young , Volume 19 , Issue 4 , August 2009 , pp. 410 - 412
Copyright
Copyright © Cambridge University Press 2009

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