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Tracheotomy bleeding from an unusual tracheo-arterial fistula: involvement of an aberrant right subclavian artery

Published online by Cambridge University Press:  11 June 2010

C Desvant ,
D Chevalier  and
G Mortuaire
C Desvant
Affiliation:
Department of Otorhinolaryngology and Head and Neck Surgery, Huriez Hospital, University of Lille, France
D Chevalier
Affiliation:
Department of Otorhinolaryngology and Head and Neck Surgery, Huriez Hospital, University of Lille, France
G Mortuaire*
Affiliation:
Department of Otorhinolaryngology and Head and Neck Surgery, Huriez Hospital, University of Lille, France
*
Address for correspondence: Dr Geoffrey Mortuaire, Service d'ORL de Chirurgie Cervico-faciale, Pr Chevalier, CHRU Lille, 59000, France. Fax: +33 320446220 E-mail: g-mortuaire@chru-lille.fr
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Abstract

Introduction:

The development of a tracheo-arterial fistula is a rare but severe complication of tracheotomy. The reported patient presented with such a fistula involving an aberrant right subclavian artery, termed an arteria lusoria, an aortic arch abnormality which is usually asymptomatic.

Case report:

A 30-year-old man was admitted to our institution for bleeding through his tracheotomy. He had been treated for advanced Duchenne muscular dystrophy, involving invasive assisted ventilation, since the age of 10 years. Surgical exploration and computed tomography scanning revealed a tracheo-arterial fistula involving an aberrant right subclavian artery, associated with severe scoliosis. Emergency, transient haemostasis was achieved by over-inflation of the tracheostomy tube cuff. Aneurysm ablation was successfully achieved as the result of an endovascular interventional radiology procedure.

Discussion:

Arteria lusoria is one of the most common aortic arch abnormalities. The occurrence of an aneurysm of this artery in a tracheotomised patient has not previously been described. In Duchenne muscular dystrophy patients, spinal deformities may result in thoracic compression, which may alter the anatomical relations of mediastinal vessels. Such deformities are slowly progressive. Thus, vigilance is required in the long term management of Duchenne muscular dystrophy patients with a tracheostomy.

Keywords

TracheotomyFistulaSubclavian ArteryDuchenne Dystrophy
Type
Clinical Records
Information
The Journal of Laryngology & Otology , Volume 124 , Issue 12 , December 2010 , pp. 1333 - 1336
Copyright
Copyright © JLO (1984) Limited 2010

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