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Bilateral maxillary mucoceles: an unusual presentation of cystic fibrosis

Published online by Cambridge University Press:  12 January 2012

A Qureishi ,
P Lennox  and
I Bottrill
A Qureishi*
Affiliation:
Department of Otolaryngology and Head and Neck Surgery, John Radcliffe Hospital, Oxford, UK
P Lennox
Affiliation:
Department of Otolaryngology and Head and Neck Surgery, John Radcliffe Hospital, Oxford, UK
I Bottrill
Affiliation:
Department of Otolaryngology and Head and Neck Surgery, John Radcliffe Hospital, Oxford, UK
*
Address for correspondence: Mr A Qureishi, 9 Cranbourne Close, Slough SL12XH, UK E-mail: aliqureishi@doctors.org.uk
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Abstract

Objective:

We report a rare case of bilateral maxillary mucoceles. This was the primary presentation in a child with an underlying diagnosis of cystic fibrosis.

Case report:

A five-month-old infant presented with isolated symptoms of nasal congestion. Initial examination and investigation with computed tomography identified the cause to be bilateral maxillary mucoceles. The child was investigated for cystic fibrosis and found to be positive. Given the young age and anatomy, a modified surgical approach was used to treat the mucoceles, comprising endoscopic and bilateral uncapping of the maxillary mucocele, uncinectomy, and middle meatal antrostomy. The child was then followed up with appropriate treatment for cystic fibrosis. At six-week follow up, there was no recurrence of symptoms.

Conclusion:

Maxillary mucoceles are extremely rare but can present in patients with chronic sinusitis or cystic fibrosis. To our knowledge, there are no prior reports of this condition being the primary indicator of underlying cystic fibrosis in the absence of upper respiratory tract symptoms. Doctors should be aware that mucoceles can present in very young individuals and may indicate an underlying diagnosis of cystic fibrosis. A high index of clinical suspicion will avoid delays in diagnosis and long-term management.

Keywords

Cystic FibrosisChildMaxillary SinusMucoceles
Type
Clinical Records
Information
The Journal of Laryngology & Otology , Volume 126 , Issue 3 , March 2012 , pp. 319 - 321
Copyright
Copyright © JLO (1984) Limited 2012

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References

1What is cystic fibrosis? In: http://www.cftrust.org.uk/aboutcf/whatiscf/ [12 December 2010]Google Scholar
2Gysin, C, Alothman, GA, Papsin, BC. Sinonasal disease in cystic fibrosis: clinical characteristics, diagnosis, and management. Pediatr Pulmonol 2000;30:481–93.0.CO;2-N>CrossRefGoogle ScholarPubMed
3Di Cicco, M, Costantini, D, Padoan, R, Colombo, C. Paranasal mucocoeles in children with cystic fibrosis. Int J Pediatr Otorhinolaryngol 2005;69:1407–13Google Scholar
4Guttenplan, M, Wetmore, R. Paranasal sinus mucocele in cystic fibrosis. Clin Pediatr 1989;28:429–30CrossRefGoogle ScholarPubMed
5Paranasal sinus mucocoele. In: http://radiopaedia.org/articles/paranasal-sinus-mucocoele [12 December 2010]Google Scholar
6Kosko, JR, Hall, BE, Tunkel, DE. Acquired maxillary sinus hypoplasia: a consequence of endoscopic sinus surgery? Laryngoscope 1996;106:1210–13CrossRefGoogle ScholarPubMed
7Sciarretta, V, Pasquini, E, Farneti, G, Ceroni, AR. Endoscopic treatment of paranasal sinus mucoceles in children. Int J Pediatr Otorhinolaryngol 2004;68:955–60CrossRefGoogle ScholarPubMed
8Olze, H, Matthias, C, Degenhardt, P. Paediatric paranasal sinus mucocoeles. Eur J Pediatr Surg 2006;16:192–6CrossRefGoogle Scholar
9Bockmühl, U, Kratzsch, B, Benda, K, Draf, W. Paranasal sinus mucoceles: surgical management and long term results [in German]. Laryngorhinootologie 2005;84:892–8CrossRefGoogle ScholarPubMed
10Robertson, JM, Friedman, EM, Rubin, BK. Nasal and sinus disease in cystic fibrosis. Paediatr Respir Rev 2008;9:213–19CrossRefGoogle ScholarPubMed