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Rapid recurrence of an inflammatory myofibroblastic tumor in the right ventricular outflow tract

Published online by Cambridge University Press:  19 August 2008

István L. Hartyánszky ,
Krisztina Kádár  and
Márta Hubay
István L. Hartyánszky*
Affiliation:
Hungarian Institute of cardiology, Budapest, Hungary
Krisztina Kádár
Affiliation:
Hungarian Institute of cardiology, Budapest, Hungary
Márta Hubay
Affiliation:
Semmelweis School of Medicine, Department of Forensic Medicine, Budapest, Hungary
*
Prof.István L.Hartyánszky MD.PhD, Hungarian Institute of Cardiology, Paediatric Cardiac Surgery Department, 1096 Budapest Halleru.29.Hungary. Tel: (1) 2151–220; Fax: (1) 2157–067; E-mail: hartyanszky@hotmail.com
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Abstract

We describe an unusual case of rapid recurrence of a previously excised inflammatory myofibroblastic tumor of the right ventricular outflow tract in a 5-month-old infant. The infant is asymptomatic 18 months after the second surgery. The very rare cardiac involvement, and the early relapse of the inflammatory pseudotumor, to the best of our knowledge, is a unique combination.

The inflammatory myofibroblastic tumor, as known as a pseudotumor or plasma cell granuloma is an uncommon reactive lesion with unknown aetiology. It is found most commonly in the lung and a number of visceral organs, such as the spleen, liver, ileum, salivary glands, urinary bladder, larynx or brain or in the retroperitoneum and lymph nodes. To our knowledge only 9 cases have been published of such tumor arising within the heart.1–6

Keywords

Cardiac inflammatory myofibroblastic tumorinflammatory pseudotumorpaediatric cardiology
Type
Brief Reports
Information
Cardiology in the Young , Volume 10 , Issue 3 , May 2000 , pp. 271 - 274
Copyright
Copyright © Cambridge University Press 2000

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References

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